Living with orofacial conditions: psychological distress and quality of life in adults affected with Treacher Collins syndrome, cherubism, or oligodontia/ectodermal dysplasia—a comparative study
Geirdal, Amy Østertun; Saltnes, Solfrid Sørgjerd; Storhaug, Kari; Åsten, Pamela; Nordgarden, Hilde; Jensen, Janicke Liaaen
Journal article, Peer reviewed, Journal article
Published version
Date
2015Metadata
Show full item recordCollections
Original version
Quality of Life Research 2015, 24(4):927-935 http://dx.doi.org/10.1007/s11136-014-0826-1Abstract
Purpose
The relationship between quality of life, psychological distress, and orofacial syndromes in children and adolescents has been reported in several studies. However, little is known about differences in psychological distress and quality of life among adults with different orofacial conditions. Therefore, the aims of this study were to examine and compare these factors among three groups of adults affected by Treacher Collins syndrome (TCS), cherubism, and oligodontia/ectodermal dysplasia (ED).
Methods
We included 11 individuals with TCS (mean age 46.9, SD 12.9 years), 15 with cherubism (mean age 50.3, SD 16.8 years), and 49 with oligodontia/ED (mean age 30.7, SD 15.6 years). The respondents completed questionnaires related to psychological distress and quality of life.
Results
The oligodontia/ED group had a significantly higher level of anxiety and worse mental health-related quality of life than both the TCS and cherubism groups. Adults with TCS reported the highest level of depression, and the lowest levels of overall quality of life, well-being, and physical health-related quality of life. The cherubism group displayed the best overall quality of life, well-being, and mental health.
Conclusions
Psychological distress and quality of life differed in various orofacial conditions. This study provided insight into these aspects that may contribute to improved care.